دورية أكاديمية

Kimura Disease of the Periorbita and Earlobe in a 15-Year-Old Male: A Case Report and Review of the Literature

التفاصيل البيبلوغرافية
العنوان: Kimura Disease of the Periorbita and Earlobe in a 15-Year-Old Male: A Case Report and Review of the Literature
المؤلفون: Han, Michael M., Dermarkarian, Christopher R., Del Valle Estopinal, Maria D., Tao, Jeremiah P.
المصدر: Ophthalmic Plastic & Reconstructive Surgery ; volume 39, issue 1, page 26-33 ; ISSN 0740-9303
بيانات النشر: Ovid Technologies (Wolters Kluwer Health)
سنة النشر: 2022
الوصف: Purpose: The authors describe a case of Kimura disease (KD) affecting the lacrimal gland, the ipsilateral periorbita, and the contralateral earlobe. The authors also review the literature for characteristics and outcomes of KD affecting the periorbita or earlobe. Methods: The authors review retrospectively a single chart and abstract data from the English language literature. Results: A 15-year-old Samoan male presented with a left upper eyelid mass and later the contralateral earlobe and ipsilateral periorbita. Surgical resection was partially effective and normal vision and eye motility were maintained. Histopathology was consistent with KD. Thirty-seven cases of periorbital KD were identified in the literature. The average age of patients with periorbital KD was 31.9 years (standard deviation: 17.8 years), with 81.1% (30/37) of patients being male and 69.4% (25/36) Asian. Over half of periorbital KD patients had lacrimal gland involvement (51.3%; 19/37). Fifteen patients were initially treated with surgery; 3 (20%) had recurrence of the disease. Another 15 patients were initially treated with corticosteroids; 12 (80%) had recurrence of the disease. Ophthalmologic data, when reported, demonstrated that, most patients had no visual (77.8%; 14/18 patients) or motility disturbances (82.4%; 14/17 patients) but most had proptosis 71.4% (10/14). Only 4 cases of earlobe involvement in KD were identified, all in women. Conclusions: In the literature, orbital KD was rare but often affected the lacrimal gland and caused proptosis, commonly in young adult Asian males. Vision and extraocular motility were usually normal. Earlobe involvement was very rare. This unique case of KD that affected the orbit and contralateral earlobe corroborates the prior literature that KD is prone to recurrence but may not adversely affect vision or extraocular motility.
نوع الوثيقة: article in journal/newspaper
اللغة: English
DOI: 10.1097/iop.0000000000002221
DOI: 10.1097/IOP.0000000000002221
الإتاحة: https://doi.org/10.1097/iop.0000000000002221Test
رقم الانضمام: edsbas.56651B65
قاعدة البيانات: BASE